Differential association
of HLA DR genotypes with chronic, neurotoxin-mediated
illnesses: Possible genetic basis for susceptibility?
Ritchie Shoemaker, Dennis House
Center for Research on Biotoxin-Associated Illness (a
not-for-profit Corporation)
500 Market Street, Suite 102, Pocomoke City, MD 24851
ABSTRACT
The recently published paradigm of chronic biotoxin-induced
illness involves multiple-system symptoms, a neurologic
deficit as indicated by visual contrast sensitivity
measurement, and symptom resolution concomitant with vision
recovery following cholestyramine treatment to bind and
eliminate toxins. Chronic illness can follow exposure to
toxins from Ciguatera, Pfiesteria and other dinoflagellates
(dinoflagellate-related illness, DRI), Aspergillis,
Penicillium, Stachybotrys and other indoor air fungi (sick
building syndrome, SBS), nasal resident coagulase negative
Staphylococcus (CNS), and bacteria and protozoa associated
with Post-Lyme Syndrome (PLS). Because some exposed
individuals acquire only acute illness or are unaffected, we
suspected that susceptibility to chronic illness was
conferred by particular patterns of genetic polymorphisms,
perhaps those coding for antigen presentation to immune T
cells. Alleles at five loci on the class II human leukocyte
antigen (HLA) genome were identified with commercial PCR
analyses, 2 alleles for DRB1, DQ and DRB3, and 1 allele for
DRB4 and DRB5, for 200 chronically ill patients with well
established exposure potentials.
In each of the four patient
classes, analyses identified unique and disproportionate
patterns of HLA alleles within the patients' entire sets of
alleles, relative to the entire patient population and to
published frequencies in a large normal population.
Statistically significant differences in allele fingerprints
were: DRI - DRB1-4, DQ-8, DRB4-53; SBS - DRB1-7 or 17, DQ-2,
DRB3-52A; CNS - DRB1-11, DQ-7, DRB3-52B; and PLS - DRB1-15,
DQ-6, DRB5-51. The specific allele pattern was present in
about 90% of patients in each class, and only about 5% of
patients also showed an allele pattern associated with
another patient class. The few patients with illness
suspected to involve two types of exposure had allele
patterns associated with risk from both types of exposure.
In addition, several patients with histories of illness in
more than one of the patient classes showed another allele
pattern, DRB1-14, DQ-5 and DRB3-52B. Preliminary data
indicated that the biotoxin exposure associated with each
patient class and allele pattern may also be associated with
a distinct pattern of elevation in proinflammatory
cytokines.
These preliminary results
suggest that distinct genetic patterns may be risk factors
for chronic illness from exposure to particular classes of
biotoxins. Susceptibility may involve cloaked or
inappropriate presentation of antigens to T cells, and
ensuing ineffective antibody production. A larger
patient-population study that includes a prospective
component is needed to confirm the possibility that
particular HLA genotypes are risk factors for acquisition of
chronic, neurotoxin-mediated illness, and to investigate the
possible roles of proinflammatory cytokines in the toxic
modes of action. Chronic inflammation is a known risk factor
for development of a variety of diseases.